Stephan Sanders, PhD
Associate Professor
Psychiatry
School of Medicine
stephan.sanders@ucsf.edu 415-502-2505
Dr. Sanders trained as a pediatric physician in the UK before undertaking a PhD and postdoctoral research position at Yale. He is now an Associate Professor at UCSF in the Department of Psychiatry. His research focuses on using genomics and bioinformatics to understand the etiology of developmental disorders, such as Autism Spectrum Disorder (ASD).
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As a member of Dr. Matthew State's lab, he worked with the Simons Simplex Collection Genomic Consortium (SSCGC) to quantify the role of de novo copy number variants (CNVs) in ASD, including discovering that de novo duplications at 7q11.23 are an ASD risk factor (Sanders et al. Neuron 2011). He also used exome sequencing to show that de novo protein-truncating variants PTVs (also called loss-of-function (LoF) mutations) are associated with ASD. This analysis established a statistical framework for identifying the specific genes involved in ASD pathology, based on these de novo events, discovering that the voltage-gated sodium channel SCN2A is an ASD risk gene (Sanders et al. Nature 2012).
Combining data from the Simons Simplex Collection (SSC), Autism Sequencing Consortium (ASC), and the Autism Genome Project (AGP), Dr. Sanders’ work identified 65 ASD-associated genes and 6 ASD-associated CNV loci (Sanders et al. Neuron 2015). In addition, by comparing the CNV and exome data, this analysis showed that a single critical gene is often present in small de novo deletions (e.g. <7 genes), whereas large de novo CNVs tend to contain multiple risk genes of lower effect.
As a PI, Dr. Sanders co-leads the whole-genome sequencing (WGS) working group of the ASC with Michael Talkowski). This group developed the Category-Wide Association Study (CWAS) approach to WGS analysis, which provides a framework to define and account for the multiple comparisons inherent to these analyses (Werling et al. Nature Genetics 2018). He is also a member of the Whole-Genome Sequencing in Psychiatric Disorders (WGSPD) steering group, which seeks to integrate WGS data across multiple disorders to maximize power (Sanders et al. Nature Neuroscience 2018).
His lab has helped understand the role of SCN2A mutations in human disorders. In collaboration with Dr. Kevin Bender, he showed that loss-of-function variants that reduce neuronal excitability lead to ASD and developmental delay, while gain-of-function variants that increase neuronal excitability lead to infantile seizures (Ben-Shalom et al. Biological Psychiatry 2017). The loss-of-function mutations also impact back-propagation of the action potential and synaptic plasticity (Spratt et al. BioRxiv 2018), potentially opening an avenue to future therapeutics, as discussed in the review written in collaboration with the SCN2A family group and numerous researchers (Sanders et al. Trends in Neuroscience 2018).
Dr. Sanders is the Director of the Psychiatry Department Bioinformatics Core (PsychCore) at UCSF, a member of the SPARK medical genetics committee, the Autism Science Foundation Scientific Advisory Board, and a Section Editor for the Journal of Neurodevelopmental Disorders.
Awards
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- Theodore Reich Young Investigator Award, International Society of Psychiatric Genetics, 2019
- UCSF Weill Neurosciences Innovation Award, UCSF Weill Institute for Neurosciences, 2016
- Annual Top 10 Autism Research Papers, Autism Speaks, 2015
- NARSAD Young Investigator Grant, Brain & Behavior Research Foundation, 2015
- International Student Research Fellowship, Howard Hughes Medical Institute (HHMI), 2013
- Gruber Science Fellowship, Gruber Foundation, 2012
Education & Training
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- PhD - supervisor: Matt State Genetics Yale 2014
- Postdoc - supervisor: Matt State Child Study Center Yale 2011
- MRCPCH (Board equivalent) Paediatrics Royal College of Paediatrics and Child Health (UK) 2007
- BMBS (MD equivalent) Medicine Nottingham Medical School (UK) 2003
Interests
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- Sodium channel
- voltage-gated
- type II
- alpha (SCN2A)
- Data analysis
- Bioinformatics
- Prematurity
- Miscarriage
- Childhood-onset Schizophrenia (COS)
- Congenital Malformations
- Autism Spectrum Disorder (ASD)
- De novo variation
- Genomics
- High-throughput sequencing
Websites
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- BRIDGE EHR platform (bridge.ucsf.edu)
- State Lab website (statelab.ucsf.edu)
- Sanders Lab website (sanderslab.ucsf.edu)
Grants and Projects
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- Assessing Genomic, Regulatory and Transcriptional Variation at Single Nuclei Resolution in the Brains of Individuals with Autism Spectrum Disorder, NIH, 2021-2026
- 2/2 - Identification and Validation of Expression Quantitative Trait Loci (eQTLs) in discrete cell types across human brain development, NIH, 2021-2025
- 4/4 - The Autism Sequencing Consortium: Autism Gene Discovery in >50,000 Exomes, NIH, 2017-2022
- 3/3 Integrative Genomic Analysis of Human Brain Development and Autism, NIH, 2016-2020
- 1/3 Multidimensional investigation of the etiology of autism spectrum disorder, NIH, 2016-2019
Publications (175)
Top publication keywords:
Autistic DisorderAutism Spectrum DisorderExomeNeurodevelopmental DisordersNAV1.2 Voltage-Gated Sodium ChannelWhole Genome SequencingVoltage-Gated Sodium ChannelsDNA Copy Number VariationsChild Development Disorders, PervasiveCOUP Transcription Factor IIWT1 ProteinsAtlases as TopicFetal TherapiesGenetic Predisposition to DiseaseProtein Tyrosine Phosphatase, Non-Receptor Type 11
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Genome-wide de novo risk score implicates promoter variation in autism spectrum disorder.
Science (New York, N.Y.) 2018 An JY, Lin K, Zhu L, Werling DM, Dong S, Brand H, Wang HZ, Zhao X, Schwartz GB, Collins RL, Currall BB, Dastmalchi C, Dea J, Duhn C, Gilson MC, Klei L, Liang L, Markenscoff-Papadimitriou E, Pochareddy… -
An analytical framework for whole-genome sequence association studies and its implications for autism spectrum disorder.
Nature genetics 2018 Werling DM, Brand H, An JY, Stone MR, Zhu L, Glessner JT, Collins RL, Dong S, Layer RM, Markenscoff-Papadimitriou E, Farrell A, Schwartz GB, Wang HZ, Currall BB, Zhao X, Dea J, Duhn C, Erdman CA, … -
Progress in Understanding and Treating SCN2A-Mediated Disorders.
Trends in neurosciences 2018 Sanders SJ, Campbell AJ, Cottrell JR, Moller RS, Wagner FF, Auldridge AL, Bernier RA, Catterall WA, Chung WK, Empfield JR, George AL, Hipp JF, Khwaja O, Kiskinis E, Lal D, Malhotra D, Millichap JJ, … -
Insights into Autism Spectrum Disorder Genomic Architecture and Biology from 71 Risk Loci.
Neuron 2015 Sanders SJ, He X, Willsey AJ, Ercan-Sencicek AG, Samocha KE, Cicek AE, Murtha MT, Bal VH, Bishop SL, Dong S, Goldberg AP, Jinlu C, Keaney JF, Klei L, Mandell JD, Moreno-De-Luca D, Poultney CS, … -
CROSS-DISORDER RARE VARIANT ANALYSIS OF AUTISM AND ADHD.
European Neuropsychopharmacology 2024 Jinjie Duan, Jakob Grove, Ditte Demontis, F. Kyle Satterstrom, Jack Fu, Caitlin Carey, Stephan Sanders, Bernie Devlin, Kathryn Roeder, Joseph Buxbaum, Elise Robinson, Michael Talkowski, Benjamin Neale…
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THE ALLELIC ARCHITECTURE OF RARE VARIATION IN AUTISM AND OTHER NEURODEVELOPMENTAL CONDITIONS.
European Neuropsychopharmacology 2024 Jack Fu, F. Kyle Satterstrom, Kirsty McWalter, Harrison Brand, Robert Kueffner, David Cutler, Kaitlin Samocha, Elise Robinson, Joseph Buxbaum, Bernie Devlin, Kathryn Roeder, Paul Kruszka, Stephan … -
Nr2f1 enhancers have distinct functions in controlling Nr2f1 expression during cortical development.
Proceedings of the National Academy of Sciences of the United States of America 2024 Liu Z, Ypsilanti AR, Markenscoff-Papadimitriou E, Dickel DE, Sanders SJ, Dong S, Pennacchio LA, Visel A, Rubenstein JL -
Multiplex, single-cell CRISPRa screening for cell type specific regulatory elements.
Nature communications 2024 Chardon FM, McDiarmid TA, Page NF, Daza RM, Martin BK, Domcke S, Regalado SG, Lalanne JB, Calderon D, Li X, Starita LM, Sanders SJ, Ahituv N, Shendure J -
The Conundrum of Mechanics Versus Genetics in Congenital Hydrocephalus and Its Implications for Fetal Therapy Approaches: A Scoping Review.
Prenatal diagnosis 2024 Herzeg A, Borges B, Diafos LN, Gupta N, MacKenzie TC, Sanders SJ -
LARP1 haploinsufficiency is associated with an autosomal dominant neurodevelopmental disorder.
HGG advances 2024 Chettle J, Louie RJ, Larner O, Best R, Chen K, Morris J, Dedeic Z, Childers A, Rogers RC, DuPont BR, Skinner C, Küry S, Uguen K, Planes M, Monteil D, Li M, Eliyahu A, Greenbaum L, Mor N, Besnard T, … -
De novo variants in the RNU4-2 snRNA cause a frequent neurodevelopmental syndrome.
Nature 2024 Chen Y, Dawes R, Kim HC, Ljungdahl A, Stenton SL, Walker S, Lord J, Lemire G, Martin-Geary AC, Ganesh VS, Ma J, Ellingford JM, Delage E, D'Souza EN, Dong S, Adams DR, Allan K, Bakshi M, Baldwin EE, … -
Examining Sex Differences in Autism Heritability.
JAMA psychiatry 2024 Sandin S, Yip BHK, Yin W, Weiss LA, Dougherty JD, Fass S, Constantino JN, Hailin Z, Turner TN, Marrus N, Gutmann DH, Sanders SJ, Christoffersson B -
Five autism-associated transcriptional regulators target shared loci proximal to brain-expressed genes.
Cell reports 2024 Fazel Darbandi S, An JY, Lim K, Page NF, Liang L, Young DM, Ypsilanti AR, State MW, Nord AS, Sanders SJ, Rubenstein JLR -
CWAS-Plus: estimating category-wide association of rare noncoding variation from whole-genome sequencing data with cell-type-specific functional data.
Briefings in bioinformatics 2024 Kim Y, Jeong M, Koh IG, Kim C, Lee H, Kim JH, Yurko R, Kim IB, Park J, Werling DM, Sanders SJ, An JY -
Haploinsufficiency underlies the neurodevelopmental consequences of SLC6A1 variants.
American journal of human genetics 2024 Silva DB, Trinidad M, Ljungdahl A, Revalde JL, Berguig GY, Wallace W, Patrick CS, Bomba L, Arkin M, Dong S, Estrada K, Hutchinson K, LeBowitz JH, Schlessinger A, Johannesen KM, Møller RS, Giacomini KM… -
A comprehensive AI model development framework for consistent Gleason grading.
Communications medicine 2024 Huo X, Ong KH, Lau KW, Gole L, Young DM, Tan CL, Zhu X, Zhang C, Zhang Y, Li L, Han H, Lu H, Zhang J, Hou J, Zhao H, Gan H, Yin L, Wang X, Chen X, Lv H, Cao H, Yu X, Shi Y, Huang Z, Marini G, Xu J, … -
Multiplex, single-cell CRISPRa screening for cell type specific regulatory elements.
bioRxiv : the preprint server for biology 2024 Chardon FM, McDiarmid TA, Page NF, Daza RM, Martin B, Domcke S, Regalado SG, Lalanne JB, Calderon D, Li X, Starita LM, Sanders SJ, Ahituv N, Shendure J -
Sex-Differential Gene Expression in Developing Human Cortex and Its Intersection With Autism Risk Pathways.
Biological psychiatry global open science 2024 Kissel LT, Pochareddy S, An JY, Sestan N, Sanders SJ, Wang X, Werling DM -
Massively parallel reporter assays and mouse transgenic assays provide complementary information about neuronal enhancer activity.
bioRxiv : the preprint server for biology 2024 Kosicki M, Cintrón DL, Page NF, Georgakopoulos-Soares I, Akiyama JA, Plajzer-Frick I, Novak CS, Kato M, Hunter RD, von Maydell K, Barton S, Godfrey P, Beckman E, Sanders SJ, Pennacchio LA, Ahituv N -
CWAS-Plus: Estimating category-wide association of rare noncoding variation from whole-genome sequencing data with cell-type-specific functional data.
medRxiv : the preprint server for health sciences 2024 Kim Y, Jeong M, Koh IG, Kim C, Lee H, Kim JH, Yurko R, Kim IB, Park J, Werling DM, Sanders SJ, An JY -
De novo variants in the non-coding spliceosomal snRNA gene RNU4-2 are a frequent cause of syndromic neurodevelopmental disorders.
medRxiv : the preprint server for health sciences 2024 Chen Y, Dawes R, Kim HC, Stenton SL, Walker S, Ljungdahl A, Lord J, Ganesh VS, Ma J, Martin-Geary AC, Lemire G, D'Souza EN, Dong S, Ellingford JM, Adams DR, Allan K, Bakshi M, Baldwin EE, Berger SI, … -
Leveraging electronic health records and knowledge networks for Alzheimer's disease prediction and sex-specific biological insights.
Nature aging 2024 Tang AS, Rankin KP, Cerono G, Miramontes S, Mills H, Roger J, Zeng B, Nelson C, Soman K, Woldemariam S, Li Y, Lee A, Bove R, Glymour M, Aghaeepour N, Oskotsky TT, Miller Z, Allen IE, Sanders SJ, … -
Thalamocortical organoids enable in vitro modeling of 22q11.2 microdeletion associated with neuropsychiatric disorders.
Cell stem cell 2024 Shin D, Kim CN, Ross J, Hennick KM, Wu SR, Paranjape N, Leonard R, Wang JC, Keefe MG, Pavlovic BJ, Donohue KC, Moreau C, Wigdor EM, Larson HH, Allen DE, Cadwell CR, Bhaduri A, Popova G, Bearden CE, … -
Prenatal delivery of a therapeutic antisense oligonucleotide achieves broad biodistribution in the brain and ameliorates Angelman syndrome phenotype in mice.
Molecular therapy : the journal of the American Society of Gene Therapy 2024 Clarke MT, Remesal L, Lentz L, Tan DJ, Young D, Thapa S, Namuduri SR, Borges B, Kirn G, Valencia J, Lopez ME, Lui JH, Shiow LR, Dindot S, Villeda S, Sanders SJ, MacKenzie TC -
Physical and functional convergence of the autism risk genes Scn2a and Ank2 in neocortical pyramidal cell dendrites.
Neuron 2024 Nelson AD, Catalfio AM, Gupta JP, Min L, Caballero-Florán RN, Dean KP, Elvira CC, Derderian KD, Kyoung H, Sahagun A, Sanders SJ, Bender KJ, Jenkins PM -
The Human Phenotype Ontology in 2024: phenotypes around the world.
Nucleic acids research 2024 Gargano MA, Matentzoglu N, Coleman B, Addo-Lartey EB, Anagnostopoulos AV, Anderton J, Avillach P, Bagley AM, Bakštein E, Balhoff JP, Baynam G, Bello SM, Berk M, Bertram H, Bishop S, Blau H, Bodenstein… -
Artificial intelligence-assisted quantification and assessment of whole slide images for pediatric kidney disease diagnosis.
Bioinformatics (Oxford, England) 2024 Feng C, Ong K, Young DM, Chen B, Li L, Huo X, Lu H, Gu W, Liu F, Tang H, Zhao M, Yang M, Zhu K, Huang L, Wang Q, Marini GPL, Gui K, Han H, Sanders SJ, Li L, Yu W, Mao J -
Predictive Modeling Leveraging Electronic Health Records Identifies Early Predictors of Alzheimer’s Disease.
Alzheimer's & Dementia 2023 Alice S Tang, Katherine P Rankin, Gabriel Cerano, Silvia Miramontes, Hunter Mills, Tomiko Oskotsky, Billy Zeng, Charlotte Nelson, Karthik Soman, Sarah Woldemariam, Yaqiao Li, Albert M Lee, Zachary … -
A Cre-dependent massively parallel reporter assay allows for cell-type specific assessment of the functional effects of non-coding elements in vivo.
Communications biology 2023 Lagunas T, Plassmeyer SP, Fischer AD, Friedman RZ, Rieger MA, Selmanovic D, Sarafinovska S, Sol YK, Kasper MJ, Fass SB, Aguilar Lucero AF, An JY, Sanders SJ, Cohen BA, Dougherty JD -
AlphaMissense is better correlated with functional assays of missense impact than earlier prediction algorithms.
bioRxiv : the preprint server for biology 2023 Ljungdahl A, Kohani S, Page NF, Wells ES, Wigdor EM, Dong S, Sanders SJ -
Astrocytic β-catenin signaling via TCF7L2 regulates synapse development and social behavior.
Molecular psychiatry 2023 Szewczyk LM, Lipiec MA, Liszewska E, Meyza K, Urban-Ciecko J, Kondrakiewicz L, Goncerzewicz A, Rafalko K, Krawczyk TG, Bogaj K, Vainchtein ID, Nakao-Inoue H, Puscian A, Knapska E, Sanders SJ, Jan … -
CHARACTERIZING ASSOCIATIONS BETWEEN DISRUPTIVE DE NOVO RARE VARIANT BURDENS AND PHENOTYPIC COMBINATIONS IN OVER 3,000 AUTISTIC CHILDREN: TOWARDS BUILDING A PUBLIC CLINICAL GENETIC RESOURCE.
European Neuropsychopharmacology 2023 Susan Kuo, Celia van der Merwe, Jack Fu, Michael Talkowski, Audrey Thurm, Stephan Sanders, Somer Bishop, Elise Robinson -
T63. CROSS-DISORDER ANALYSIS OF AUTISM AND ADHD USING RARE VARIANTS: INSIGHTS FROM DANISH IPSYCH EXOMES.
European Neuropsychopharmacology 2023 Jinjie Duan, Jakob Grove, Ditte Demontis, F. Kyle Satterstrom, Jack Fu, Caitlin Carey, Stephan J. Sanders, Bernie Devlin, Kathryn Roeder, Joseph Buxbaum, Elise Robinson, Michael Talkowski, Benjamin … -
Neuropsychiatric biomarker discovery: go big or go home.
Trends in molecular medicine 2023 Ljungdahl A, Sanders SJ -
Systematic identification of disease-causing promoter and untranslated region variants in 8,040 undiagnosed individuals with rare disease.
medRxiv : the preprint server for health sciences 2023 Martin-Geary AC, Blakes AJM, Dawes R, Findlay SD, Lord J, Walker S, Talbot-Martin J, Wieder N, D'Souza EN, Fernandes M, Hilton S, Lahiri N, Campbell C, Jenkinson S, DeGoede CGEL, Anderson ER, Burge CB… -
Systematic evaluation of genome sequencing for the diagnostic assessment of autism spectrum disorder and fetal structural anomalies.
American journal of human genetics 2023 Lowther C, Valkanas E, Giordano JL, Wang HZ, Currall BB, O'Keefe K, Pierce-Hoffman E, Kurtas NE, Whelan CW, Hao SP, Weisburd B, Jalili V, Fu J, Wong I, Collins RL, Zhao X, Austin-Tse CA, Evangelista E… -
KCNT2-Related Disorders: Phenotypes, Functional, and Pharmacological Properties.
Annals of neurology 2023 Cioclu MC, Mosca I, Ambrosino P, Puzo D, Bayat A, Wortmann SB, Koch J, Strehlow V, Shirai K, Matsumoto N, Sanders SJ, Michaud V, Legendre M, Riva A, Striano P, Muhle H, Pendziwiat M, Lesca G, Mangano … -
Characterization of De Novo Promoter Variants in Autism Spectrum Disorder with Massively Parallel Reporter Assays.
International journal of molecular sciences 2023 Koesterich J, An JY, Inoue F, Sohota A, Ahituv N, Sanders SJ, Kreimer A -
In Search of Biomarkers to Guide Interventions in Autism Spectrum Disorder: A Systematic Review.
The American journal of psychiatry 2022 Parellada M, Andreu-Bernabeu Á, Burdeus M, San José Cáceres A, Urbiola E, Carpenter LL, Kraguljac NV, McDonald WM, Nemeroff CB, Rodriguez CI, Widge AS, State MW, Sanders SJ -
Spatiotemporal and genetic regulation of A-to-I editing throughout human brain development.
Cell reports 2022 Cuddleston WH, Fan X, Sloofman L, Liang L, Mossotto E, Moore K, Zipkowitz S, Wang M, Zhang B, Wang J, Sestan N, Devlin B, Roeder K, Sanders SJ, Buxbaum JD, Breen MS -
Prenatal Somatic Cell Gene Therapies: Charting a Path Toward Clinical Applications (Proceedings of the CERSI-FDA Meeting).
Journal of clinical pharmacology 2022 Herzeg A, Almeida-Porada G, Charo RA, David AL, Gonzalez-Velez J, Gupta N, Lapteva L, Lianoglou B, Peranteau W, Porada C, Sanders SJ, Sparks TN, Stitelman DH, Struble E, Sumner CJ, MacKenzie TC -
Rare coding variation provides insight into the genetic architecture and phenotypic context of autism.
Nature genetics 2022 Fu JM, Satterstrom FK, Peng M, Brand H, Collins RL, Dong S, Wamsley B, Klei L, Wang L, Hao SP, Stevens CR, Cusick C, Babadi M, Banks E, Collins B, Dodge S, Gabriel SB, Gauthier L, Lee SK, Liang L, … -
The female protective effect against autism spectrum disorder.
Cell genomics 2022 Wigdor EM, Weiner DJ, Grove J, Fu JM, Thompson WK, Carey CE, Baya N, van der Merwe C, Walters RK, Satterstrom FK, Palmer DS, Rosengren A, Bybjerg-Grauholm J, iPSYCH Consortium, Hougaard DM, Mortensen … -
Enhancing Clinical Information Display to Improve Patient Encounters: Human-Centered Design and Evaluation of the Parkinson Disease-BRIDGE Platform.
JMIR human factors 2022 Brown EG, Schleimer E, Bledsoe IO, Rowles W, Miller NA, Sanders SJ, Rankin KP, Ostrem JL, Tanner CM, Bove R -
A Biomedical Open Knowledge Network Harnesses the Power of AI to Understand Deep Human Biology.
AI Magazine 2022 Sergio Baranzini, Katy Börner, John Morris, Charlotte Nelson, Karthik Soman, Erica Schleimer, Michael Keiser, Mark Musen, Roger Pearce, Tahsin Reza, Brett Smith, Bruce Herr II, Boris Oskotsky, Angela … -
A biomedical open knowledge network harnesses the power of AI to understand deep human biology.
AI magazine 2022 Baranzini SE, Börner K, Morris J, Nelson CA, Soman K, Schleimer E, Keiser M, Musen M, Pearce R, Reza T, Smith B, Herr BW, Oskotsky B, Rizk-Jackson A, Rankin KP, Sanders SJ, Bove R, Rose PW, Israni S, … -
Detection of subtle white matter lesions in MRI through texture feature extraction and boundary delineation using an embedded clustering strategy.
Scientific reports 2022 Ong K, Young DM, Sulaiman S, Shamsuddin SM, Mohd Zain NR, Hashim H, Yuen K, Sanders SJ, Yu W, Hang S -
High-throughput characterization of the role of non-B DNA motifs on promoter function.
Cell genomics 2022 Georgakopoulos-Soares I, Victorino J, Parada GE, Agarwal V, Zhao J, Wong HY, Umar MI, Elor O, Muhwezi A, An JY, Sanders SJ, Kwok CK, Inoue F, Hemberg M, Ahituv N -
Assessing the utility of electronic measures as a proxy for cognitive ability.
Autism Research 2022 Tess Levy, Bari Britvan, Hannah Grosman, Ivy Giserman-Kiss, Kristin Meyering, Jordana Weissman, Danielle Halpern, Jessica Zweifach, M. Pilar Trelles, Jennifer H. Foss-Feig, Alexander Kolevzon, Stephan… -
Building a Precision Medicine Delivery Platform for Clinics: The University of California, San Francisco, BRIDGE Experience.
Journal of medical Internet research 2022 Bove R, Schleimer E, Sukhanov P, Gilson M, Law SM, Barnecut A, Miller BL, Hauser SL, Sanders SJ, Rankin KP -
47. GENE DISCOVERY FROM EXOME SEQUENCING IN AUTISM AND COMPARISON TO DEVELOPMENTAL DELAY AND SCHIZOPHRENIA.
European Neuropsychopharmacology 2021 F. Kyle Satterstrom, Jack Fu, Minshi Peng, Harrison Brand, Ryan L. Collins, Shan Dong, Anders D. Børglum, Elise B. Robinson, David J. Cutler, Joseph D. Buxbaum, Mark J. Daly, Kathryn Roeder, Bernie … -
THE FEMALE PROTECTIVE EFFECT AGAINST AUTISM SPECTRUM DISORDER.
European Neuropsychopharmacology 2021 Emilie Wigdor, Daniel Weiner, Jakob Grove, Jack Fu, Wesley Thompson, Caitlin Carey, Nikolas Baya, Celia van der Merwe, Preben Bo Mortensen, Mark Daly, Michael Talkowski, Stephan Sanders, Somer Bishop,… -
Developmental dynamics of voltage-gated sodium channel isoform expression in the human and mouse brain.
Genome medicine 2021 Liang L, Fazel Darbandi S, Pochareddy S, Gulden FO, Gilson MC, Sheppard BK, Sahagun A, An JY, Werling DM, Rubenstein JLR, Sestan N, Bender KJ, Sanders SJ -
Patterns of delay in early gross motor and expressive language milestone attainment in probands with genetic conditions versus idiopathic ASD from SFARI registries.
Journal of child psychology and psychiatry, and allied disciplines 2021 Wickstrom J, Farmer C, Green Snyder L, Mitz AR, Sanders SJ, Bishop S, Thurm A -
Paradoxical hyperexcitability from NaV1.2 sodium channel loss in neocortical pyramidal cells.
Cell reports 2021 Spratt PWE, Alexander RPD, Ben-Shalom R, Sahagun A, Kyoung H, Keeshen CM, Sanders SJ, Bender KJ -
Exome sequencing of fetuses with congenital diaphragmatic hernia supports a causal role for NR2F2, PTPN11, and WT1 variants.
American journal of surgery 2021 Schwab ME, Dong S, Lianoglou BR, Aguilar Lucero AF, Schwartz GB, Norton ME, MacKenzie TC, Sanders SJ -
Extrathymic Aire-expressing cells support maternal-fetal tolerance.
Science immunology 2021 Gillis-Buck E, Miller H, Sirota M, Sanders SJ, Ntranos V, Anderson MS, Gardner JM, MacKenzie TC -
Exome Sequencing for Prenatal Diagnosis in Nonimmune Hydrops Fetalis.
Obstetric Anesthesia Digest 2021 T.N. Sparks, B.R. Lianoglou, R.R. Adami, I.D. Pluym, K. Holliman, K. Duffy, S.L. Downum, S. Patel, A. Faubel, N.M. Boe, N.T. Field, A. Murphy, L.C. Laurent, J. Jolley, C. Uy, A.M. Slavotinek, P. … -
Prenatal exposure to paternal smoking and likelihood for autism spectrum disorder.
Autism : the international journal of research and practice 2021 Kim B, Ha M, Kim YS, Koh YJ, Dong S, Kwon HJ, Kim YS, Lim MH, Paik KC, Yoo SJ, Kim H, Hong PS, Sanders SJ, Leventhal BL -
A model and test for coordinated polygenic epistasis in complex traits.
Proceedings of the National Academy of Sciences of the United States of America 2021 Sheppard B, Rappoport N, Loh PR, Sanders SJ, Zaitlen N, Dahl A -
16p11.2.
2021 Stephan Sanders -
7q11.23 Duplications.
2021 Stephan Sanders -
Multiplex-Simplex Comparisons.
2021 Stephan Sanders -
De novo structural mutation rates and gamete-of-origin biases revealed through genome sequencing of 2,396 families.
American journal of human genetics 2021 Belyeu JR, Brand H, Wang H, Zhao X, Pedersen BS, Feusier J, Gupta M, Nicholas TJ, Brown J, Baird L, Devlin B, Sanders SJ, Jorde LB, Talkowski ME, Quinlan AR -
Exome Sequencing for Prenatal Diagnosis in Nonimmune Hydrops Fetalis.
Obstetrical & Gynecological Survey 2021 Teresa N. Sparks, Billie R. Lianoglou, Rebecca R. Adami, Ilina D. Pluym, Kerry Holliman, Jennifer Duffy, Sarah L. Downum, Sachi Patel, Amanda Faubel, Nina M. Boe, Nancy T. Field, Aisling Murphy, … -
Constructing and optimizing 3D atlases from 2D data with application to the developing mouse brain.
eLife 2021 Young DM, Fazel Darbandi S, Schwartz G, Bonzell Z, Yuruk D, Nojima M, Gole LC, Rubenstein JL, Yu W, Sanders SJ -
Whole-Brain Image Analysis and Anatomical Atlas 3D Generation Using MagellanMapper.
Current protocols in neuroscience 2020 Young DM, Duhn C, Gilson M, Nojima M, Yuruk D, Kumar A, Yu W, Sanders SJ -
Not All Autism Genes Are Created Equal: A Response to Myers et al.
American journal of human genetics 2020 Buxbaum JD, Cutler DJ, Daly MJ, Devlin B, Roeder K, Sanders SJ, Autism Sequencing Consortium -
Exome Sequencing for Prenatal Diagnosis in Nonimmune Hydrops Fetalis.
The New England journal of medicine 2020 Sparks TN, Lianoglou BR, Adami RR, Pluym ID, Holliman K, Duffy J, Downum SL, Patel S, Faubel A, Boe NM, Field NT, Murphy A, Laurent LC, Jolley J, Uy C, Slavotinek AM, Devine P, Hodoglugil U, Van … -
Whole-Exome Sequencing in Fetuses with Congenital Diaphragmatic Hernias: Known and Novel Genetic Mutation.
Journal of the American College of Surgeons 2020 Marisa E. Schwab, Shan Dong, Stephan J. Sanders, Tippi C. MacKenzie -
Homeostatic plasticity fails at the intersection of autism-gene mutations and a novel class of common genetic modifiers.
eLife 2020 Genç Ö, An JY, Fetter RD, Kulik Y, Zunino G, Sanders SJ, Davis GW -
A Chromatin Accessibility Atlas of the Developing Human Telencephalon.
Cell 2020 Markenscoff-Papadimitriou E, Whalen S, Przytycki P, Thomas R, Binyameen F, Nowakowski TJ, Kriegstein AR, Sanders SJ, State MW, Pollard KS, Rubenstein JL -
Clinical impact of splicing in neurodevelopmental disorders.
Genome medicine 2020 Sanders SJ, Schwartz GB, Farh KK -
Whole-Genome and RNA Sequencing Reveal Variation and Transcriptomic Coordination in the Developing Human Prefrontal Cortex.
Cell reports 2020 Werling DM, Pochareddy S, Choi J, An JY, Sheppard B, Peng M, Li Z, Dastmalchi C, Santpere G, Sousa AMM, Tebbenkamp ATN, Kaur N, Gulden FO, Breen MS, Liang L, Gilson MC, Zhao X, Dong S, Klei L, Cicek … -
Biological concepts in human sodium channel epilepsies and their relevance in clinical practice.
Epilepsia 2020 Brunklaus A, Du J, Steckler F, Ghanty II, Johannesen KM, Fenger CD, Schorge S, Baez-Nieto D, Wang HR, Allen A, Pan JQ, Lerche H, Heyne H, Symonds JD, Zuberi SM, Sanders S, Sheidley BR, Craiu D, Olson … -
Large-Scale Exome Sequencing Study Implicates Both Developmental and Functional Changes in the Neurobiology of Autism.
Cell 2020 Satterstrom FK, Kosmicki JA, Wang J, Breen MS, De Rubeis S, An JY, Peng M, Collins R, Grove J, Klei L, Stevens C, Reichert J, Mulhern MS, Artomov M, Gerges S, Sheppard B, Xu X, Bhaduri A, Norman U, … -
83: HyDROPS study: Exome sequencing identifies genetic disorders causing non-immune hydrops fetalis.
American Journal of Obstetrics and Gynecology 2020 Teresa N. Sparks, Billie R. Lianoglou, Sachi Patel, Rebecca Adami, Naseem Rangwala, Ilina D. Pluym, Kerry Holliman, Sarah Downum, Jessica Amezcua, Nina M. Boe, Nancy T. Field, Renata Gallagher, Louise… -
A framework for the investigation of rare genetic disorders in neuropsychiatry.
Nature medicine 2019 Sanders SJ, Sahin M, Hostyk J, Thurm A, Jacquemont S, Avillach P, Douard E, Martin CL, Modi ME, Moreno-De-Luca A, Raznahan A, Anticevic A, Dolmetsch R, Feng G, Geschwind DH, Glahn DC, Goldstein DB, … -
Next-Generation Sequencing in Autism Spectrum Disorder.
Cold Spring Harbor perspectives in medicine 2019 Sanders SJ -
The Autism-Associated Gene Scn2a Contributes to Dendritic Excitability and Synaptic Function in the Prefrontal Cortex.
Neuron 2019 Spratt PWE, Ben-Shalom R, Keeshen CM, Burke KJ, Clarkson RL, Sanders SJ, Bender KJ -
Missense Variants in the Histone Acetyltransferase Complex Component Gene TRRAP Cause Autism and Syndromic Intellectual Disability.
American journal of human genetics 2019 Cogné B, Ehresmann S, Beauregard-Lacroix E, Rousseau J, Besnard T, Garcia T, Petrovski S, Avni S, McWalter K, Blackburn PR, Sanders SJ, Uguen K, Harris J, Cohen JS, Blyth M, Lehman A, Berg J, Li MH, … -
Predicting Splicing from Primary Sequence with Deep Learning.
Cell 2019 Jaganathan K, Kyriazopoulou Panagiotopoulou S, McRae JF, Darbandi SF, Knowles D, Li YI, Kosmicki JA, Arbelaez J, Cui W, Schwartz GB, Chow ED, Kanterakis E, Gao H, Kia A, Batzoglou S, Sanders SJ, Farh … -
31DISCOVERY AND CHARACTERIZATION OF 102 GENES ASSOCIATED WITH AUTISM FROM EXOME SEQUENCING OF 37,269 INDIVIDUALS.
European Neuropsychopharmacology 2019 Frederick Satterstrom, Jack Kosmicki, Jiebiao Wang, Ryan Collins, Silvia de Rubeis, Michael Breen, Sherif Gerges, Anders Børglum, Joseph Buxbaum, David Cutler, Bernie Devlin, Kathryn Roeder, Stephan … -
9 LIMITED CONTRIBUTION OF RARE, NONCODING VARIATION TO AUTISM SPECTRUM DISORDER FROM SEQUENCING OF 2,076 GENOMES IN QUARTET FAMILIES.
European Neuropsychopharmacology 2019 Donna Werling, Harrison Brand, Joon-Yong An, Matthew Stone, Joseph Glessner, Lingxue Zhu, Ryan Collins, Mark Daly, Matthew State, Aaron Quinlan, Gabor Marth, Kathryn Roeder, Bernie Devlin, Stephan … -
Integrative functional genomic analysis of human brain development and neuropsychiatric risks.
Science (New York, N.Y.) 2018 Li M, Santpere G, Imamura Kawasawa Y, Evgrafov OV, Gulden FO, Pochareddy S, Sunkin SM, Li Z, Shin Y, Zhu Y, Sousa AMM, Werling DM, Kitchen RR, Kang HJ, Pletikos M, Choi J, Muchnik S, Xu X, Wang D, … -
Automating Installation of the Integrating Biology and the Bedside (i2b2) Platform.
Biomedical informatics insights 2018 Wagholikar KB, Mendis M, Dessai P, Sanz J, Law S, Gilson M, Sanders S, Vangala M, Bell DS, Murphy SN -
Dual Molecular Effects of Dominant RORA Mutations Cause Two Variants of Syndromic Intellectual Disability with Either Autism or Cerebellar Ataxia.
American journal of human genetics 2018 Guissart C, Latypova X, Rollier P, Khan TN, Stamberger H, McWalter K, Cho MT, Kjaergaard S, Weckhuysen S, Lesca G, Besnard T, Õunap K, Schema L, Chiocchetti AG, McDonald M, de Bellescize J, Vincent M,… -
Whole genome sequencing in psychiatric disorders: the WGSPD consortium.
Nature neuroscience 2017 Sanders SJ, Neale BM, Huang H, Werling DM, An JY, Dong S, Whole Genome Sequencing for Psychiatric Disorders (WGSPD), Abecasis G, Arguello PA, Blangero J, Boehnke M, Daly MJ, Eggan K, Geschwind DH, … -
De Novo Mutations in Protein Kinase Genes CAMK2A and CAMK2B Cause Intellectual Disability.
American journal of human genetics 2017 Küry S, van Woerden GM, Besnard T, Proietti Onori M, Latypova X, Towne MC, Cho MT, Prescott TE, Ploeg MA, Sanders S, Stessman HAF, Pujol A, Distel B, Robak LA, Bernstein JA, Denommé-Pichon AS, Lesca G… -
Contribution of rare inherited and de novo variants in 2,871 congenital heart disease probands.
Nature genetics 2017 Jin SC, Homsy J, Zaidi S, Lu Q, Morton S, DePalma SR, Zeng X, Qi H, Chang W, Sierant MC, Hung WC, Haider S, Zhang J, Knight J, Bjornson RD, Castaldi C, Tikhonoa IR, Bilguvar K, Mane SM, Sanders SJ, … -
Children with autism spectrum disorder who improve with fever: Insights from the Simons Simplex Collection.
Autism research : official journal of the International Society for Autism Research 2017 Grzadzinski R, Lord C, Sanders SJ, Werling D, Bal VH -
Appreciating the Population-wide Impact of Copy Number Variants on Cognition.
Biological psychiatry 2017 An JY, Sanders SJ -
Polygenic transmission disequilibrium confirms that common and rare variation act additively to create risk for autism spectrum disorders.
Nature genetics 2017 Weiner DJ, Wigdor EM, Ripke S, Walters RK, Kosmicki JA, Grove J, Samocha KE, Goldstein JI, Okbay A, Bybjerg-Grauholm J, Werge T, Hougaard DM, Taylor J, iPSYCH-Broad Autism Group, Psychiatric Genomics … -
De Novo Coding Variants Are Strongly Associated with Tourette Disorder.
Neuron 2017 Willsey AJ, Fernandez TV, Yu D, King RA, Dietrich A, Xing J, Sanders SJ, Mandell JD, Huang AY, Richer P, Smith L, Dong S, Samocha KE, Tourette International Collaborative Genetics (TIC Genetics), … -
706 Wnt/ß-Catenin Pathway Contributions to Dendritic Spine and Glutamatergic Synapse Formation Responsive to Lithium-Mediated GSK3 Inhibition.
Biological Psychiatry 2017 Robert Stanley, Pierre-Marie Martin, Adam Ross, Andiara Freitas, Jillian Iafrati, Caitlin Moyer, Audrey Brumback, Mehdi Pirooznia, W. Richard McCombie, James Potash, Peter Zandi, Shaun Purcell, … -
De Novo Disruption of the Proteasome Regulatory Subunit PSMD12 Causes a Syndromic Neurodevelopmental Disorder.
American journal of human genetics 2017 Küry S, Besnard T, Ebstein F, Khan TN, Gambin T, Douglas J, Bacino CA, Craigen WJ, Sanders SJ, Lehmann A, Latypova X, Khan K, Pacault M, Sacharow S, Glaser K, Bieth E, Perrin-Sabourin L, Jacquemont ML… -
Peabody Picture Vocabulary Test: Proxy for Verbal IQ in Genetic Studies of Autism Spectrum Disorder.
Journal of autism and developmental disorders 2017 Krasileva KE, Sanders SJ, Bal VH -
Defining the diverse spectrum of inversions, complex structural variation, and chromothripsis in the morbid human genome.
Genome biology 2017 Collins RL, Brand H, Redin CE, Hanscom C, Antolik C, Stone MR, Glessner JT, Mason T, Pregno G, Dorrani N, Mandrile G, Giachino D, Perrin D, Walsh C, Cipicchio M, Costello M, Stortchevoi A, An JY, … -
Identification of Developmental and Behavioral Markers Associated With Genetic Abnormalities in Autism Spectrum Disorder.
The American journal of psychiatry 2017 Bishop SL, Farmer C, Bal V, Robinson EB, Willsey AJ, Werling DM, Havdahl KA, Sanders SJ, Thurm A -
Refining the role of de novo protein-truncating variants in neurodevelopmental disorders by using population reference samples.
Nature genetics 2017 Kosmicki JA, Samocha KE, Howrigan DP, Sanders SJ, Slowikowski K, Lek M, Karczewski KJ, Cutler DJ, Devlin B, Roeder K, Buxbaum JD, Neale BM, MacArthur DG, Wall DP, Robinson EB, Daly MJ -
Opposing Effects on NaV1.2 Function Underlie Differences Between SCN2A Variants Observed in Individuals With Autism Spectrum Disorder or Infantile Seizures.
Biological psychiatry 2017 Ben-Shalom R, Keeshen CM, Berrios KN, An JY, Sanders SJ, Bender KJ -
De Novo Disruption of the Proteasome Regulatory Subunit PSMD12 Causes a Syndromic Neurodevelopmental Disorder.
American journal of human genetics 2017 Küry S, Besnard T, Ebstein F, Khan TN, Gambin T, Douglas J, Bacino CA, Craigen WJ, Sanders SJ, Lehmann A, Latypova X, Khan K, Pacault M, Sacharow S, Glaser K, Bieth E, Perrin-Sabourin L, Jacquemont ML… -
DIXDC1 contributes to psychiatric susceptibility by regulating dendritic spine and glutamatergic synapse density via GSK3 and Wnt/β-catenin signaling.
Molecular psychiatry 2016 Martin PM, Stanley RE, Ross AP, Freitas AE, Moyer CE, Brumback AC, Iafrati J, Stapornwongkul KS, Dominguez S, Kivimäe S, Mulligan KA, Pirooznia M, McCombie WR, Potash JB, Zandi PP, Purcell SM, Sanders… -
S.33.03 Phenotype-genotype associations in the Simons Simplex Collection for autism spectrum disorder.
European Neuropsychopharmacology 2016 S. Bishop, C. Farmer, V. Hus Bal, E. Robinson, S. Sanders, A. Havdahl, A. Thurn -
Intergenerational Neuroimaging of Human Brain Circuitry.
Trends in neurosciences 2016 Ho TC, Sanders SJ, Gotlib IH, Hoeft F -
Rare Inherited and De Novo CNVs Reveal Complex Contributions to ASD Risk in Multiplex Families.
American journal of human genetics 2016 Leppa VM, Kravitz SN, Martin CL, Andrieux J, Le Caignec C, Martin-Coignard D, DyBuncio C, Sanders SJ, Lowe JK, Cantor RM, Geschwind DH -
Whole-exome sequencing in obsessive-compulsive disorder identifies rare mutations in immunological and neurodevelopmental pathways.
Translational psychiatry 2016 Cappi C, Brentani H, Lima L, Sanders SJ, Zai G, Diniz BJ, Reis VN, Hounie AG, Conceição do Rosário M, Mariani D, Requena GL, Puga R, Souza-Duran FL, Shavitt RG, Pauls DL, Miguel EC, Fernandez TV -
Frequency and Complexity of De Novo Structural Mutation in Autism.
American journal of human genetics 2016 Brandler WM, Antaki D, Gujral M, Noor A, Rosanio G, Chapman TR, Barrera DJ, Lin GN, Malhotra D, Watts AC, Wong LC, Estabillo JA, Gadomski TE, Hong O, Fajardo KV, Bhandari A, Owen R, Baughn M, Yuan J, … -
Genetic risk for autism spectrum disorders and neuropsychiatric variation in the general population.
Nature genetics 2016 Robinson EB, St Pourcain B, Anttila V, Kosmicki JA, Bulik-Sullivan B, Grove J, Maller J, Samocha KE, Sanders SJ, Ripke S, Martin J, Hollegaard MV, Werge T, Hougaard DM, iPSYCH-SSI-Broad Autism Group, … -
Attention Finally Being Paid to Girls at Risk of Autism.
Journal of the American Academy of Child and Adolescent Psychiatry 2016 Bishop SL, Veenstra-VanderWeele J, Sanders SJ -
Gene coexpression modules in human cognition.
Nature neuroscience 2016 Werling DM, Sanders SJ -
Chapter 1 The Newly Emerging View of the Genome.
Genomics, Circuits, and Pathways in Clinical Neuropsychiatry 2016 Stephan J. Sanders, Christopher E. Mason -
Chapter 29 Autism Spectrum Disorder Genes to Pathways to Circuits.
Genomics, Circuits, and Pathways in Clinical Neuropsychiatry 2016 Rebecca A. Muhle, Stephan J. Sanders, Hannah E. Reed, Matthew W. State -
De novo mutations in congenital heart disease with neurodevelopmental and other congenital anomalies.
Science (New York, N.Y.) 2015 Homsy J, Zaidi S, Shen Y, Ware JS, Samocha KE, Karczewski KJ, DePalma SR, McKean D, Wakimoto H, Gorham J, Jin SC, Deanfield J, Giardini A, Porter GA, Kim R, Bilguvar K, López-Giráldez F, Tikhonova I, … -
First glimpses of the neurobiology of autism spectrum disorder.
Current opinion in genetics & development 2015 Sanders SJ -
Paired-Duplication Signatures Mark Cryptic Inversions and Other Complex Structural Variation.
American journal of human genetics 2015 Brand H, Collins RL, Hanscom C, Rosenfeld JA, Pillalamarri V, Stone MR, Kelley F, Mason T, Margolin L, Eggert S, Mitchell E, Hodge JC, Gusella JF, Sanders SJ, Talkowski ME -
Sex and gender differences in autism spectrum disorder: summarizing evidence gaps and identifying emerging areas of priority.
Molecular autism 2015 Halladay AK, Bishop S, Constantino JN, Daniels AM, Koenig K, Palmer K, Messinger D, Pelphrey K, Sanders SJ, Singer AT, Taylor JL, Szatmari P -
The female protective effect in autism spectrum disorder is not mediated by a single genetic locus.
Molecular autism 2015 Gockley J, Willsey AJ, Dong S, Dougherty JD, Constantino JN, Sanders SJ -
Loss of δ-catenin function in severe autism.
Nature 2015 Turner TN, Sharma K, Oh EC, Liu YP, Collins RL, Sosa MX, Auer DR, Brand H, Sanders SJ, Moreno-De-Luca D, Pihur V, Plona T, Pike K, Soppet DR, Smith MW, Cheung SW, Martin CL, State MW, Talkowski ME, … -
The autism-associated chromatin modifier CHD8 regulates other autism risk genes during human neurodevelopment.
Nature communications 2015 Cotney J, Muhle RA, Sanders SJ, Liu L, Willsey AJ, Niu W, Liu W, Klei L, Lei J, Yin J, Reilly SK, Tebbenkamp AT, Bichsel C, Pletikos M, Sestan N, Roeder K, State MW, Devlin B, Noonan JP -
A MARKOV RANDOM FIELD-BASED APPROACH TO CHARACTERIZING HUMAN BRAIN DEVELOPMENT USING SPATIAL-TEMPORAL TRANSCRIPTOME DATA.
The annals of applied statistics 2015 Lin Z, Sanders SJ, Li M, Sestan N, State MW, Zhao H -
No evidence for association of autism with rare heterozygous point mutations in Contactin-Associated Protein-Like 2 (CNTNAP2), or in Other Contactin-Associated Proteins or Contactins.
PLoS genetics 2015 Murdoch JD, Gupta AR, Sanders SJ, Walker MF, Keaney J, Fernandez TV, Murtha MT, Anyanwu S, Ober GT, Raubeson MJ, DiLullo NM, Villa N, Waqar Z, Sullivan C, Gonzalez L, Willsey AJ, Choe SY, Neale BM, … -
Psychiatric genome-wide association study analyses implicate neuronal, immune and histone pathways.
Nature neuroscience 2015 Network and Pathway Analysis Subgroup of Psychiatric Genomics Consortium -
Genotype to phenotype relationships in autism spectrum disorders.
Nature neuroscience 2014 Chang J, Gilman SR, Chiang AH, Sanders SJ, Vitkup D -
Modeling non-syndromic autism and the impact of TRPC6 disruption in human neurons.
Molecular psychiatry 2014 Griesi-Oliveira K, Acab A, Gupta AR, Sunaga DY, Chailangkarn T, Nicol X, Nunez Y, Walker MF, Murdoch JD, Sanders SJ, Fernandez TV, Ji W, Lifton RP, Vadasz E, Dietrich A, Pradhan D, Song H, Ming GL, Gu… -
Synaptic, transcriptional and chromatin genes disrupted in autism.
Nature 2014 De Rubeis S, He X, Goldberg AP, Poultney CS, Samocha K, Cicek AE, Kou Y, Liu L, Fromer M, Walker S, Singh T, Klei L, Kosmicki J, Shih-Chen F, Aleksic B, Biscaldi M, Bolton PF, Brownfeld JM, Cai J, … -
The contribution of de novo coding mutations to autism spectrum disorder.
Nature 2014 Iossifov I, O'Roak BJ, Sanders SJ, Ronemus M, Krumm N, Levy D, Stessman HA, Witherspoon KT, Vives L, Patterson KE, Smith JD, Paeper B, Nickerson DA, Dea J, Dong S, Gonzalez LE, Mandell JD, Mane SM, … -
De novo insertions and deletions of predominantly paternal origin are associated with autism spectrum disorder.
Cell reports 2014 Dong S, Walker MF, Carriero NJ, DiCola M, Willsey AJ, Ye AY, Waqar Z, Gonzalez LE, Overton JD, Frahm S, Keaney JF, Teran NA, Dea J, Mandell JD, Hus Bal V, Sullivan CA, DiLullo NM, Khalil RO, Gockley J… -
A genome-wide association study of autism using the Simons Simplex Collection: Does reducing phenotypic heterogeneity in autism increase genetic homogeneity?
Biological psychiatry 2014 Chaste P, Klei L, Sanders SJ, Hus V, Murtha MT, Lowe JK, Willsey AJ, Moreno-De-Luca D, Yu TW, Fombonne E, Geschwind D, Grice DE, Ledbetter DH, Mane SM, Martin DM, Morrow EM, Walsh CA, Sutcliffe JS, … -
Increased frequency of de novo copy number variants in congenital heart disease by integrative analysis of single nucleotide polymorphism array and exome sequence data.
Circulation research 2014 Glessner JT, Bick AG, Ito K, Homsy J, Rodriguez-Murillo L, Fromer M, Mazaika E, Vardarajan B, Italia M, Leipzig J, DePalma SR, Golhar R, Sanders SJ, Yamrom B, Ronemus M, Iossifov I, Willsey AJ, State … -
Cross-Disorder Comparison of Four Neuropsychiatric CNV Loci.
Current Genetic Medicine Reports 2014 Daniel Moreno-De-Luca, Andres Moreno-De-Luca, Joseph F. Cubells, Stephan J. Sanders -
A framework for the interpretation of de novo mutation in human disease.
Nature genetics 2014 Samocha KE, Robinson EB, Sanders SJ, Stevens C, Sabo A, McGrath LM, Kosmicki JA, Rehnström K, Mallick S, Kirby A, Wall DP, MacArthur DG, Gabriel SB, DePristo M, Purcell SM, Palotie A, Boerwinkle E, … -
Cross-Disorder Comparison of Four Neuropsychiatric CNV Loci
Curr Genet Med Rep 2014 Moreno-De-Luca D, Moreno-De-Luca A, Cubells JF, Sanders SJ -
Most genetic risk for autism resides with common variation.
Nature genetics 2014 Gaugler T, Klei L, Sanders SJ, Bodea CA, Goldberg AP, Lee AB, Mahajan M, Manaa D, Pawitan Y, Reichert J, Ripke S, Sandin S, Sklar P, Svantesson O, Reichenberg A, Hultman CM, Devlin B, Roeder K, … -
Modest impact on risk for autism spectrum disorder of rare copy number variants at 15q11.2, specifically breakpoints 1 to 2.
Autism research : official journal of the International Society for Autism Research 2014 Chaste P, Sanders SJ, Mohan KN, Klei L, Song Y, Murtha MT, Hus V, Lowe JK, Willsey AJ, Moreno-De-Luca D, Yu TW, Fombonne E, Geschwind D, Grice DE, Ledbetter DH, Lord C, Mane SM, Martin DM, Morrow EM, … -
Homozygous loss of DIAPH1 is a novel cause of microcephaly in humans.
European journal of human genetics : EJHG 2014 Ercan-Sencicek AG, Jambi S, Franjic D, Nishimura S, Li M, El-Fishawy P, Morgan TM, Sanders SJ, Bilguvar K, Suri M, Johnson MH, Gupta AR, Yuksel Z, Mane S, Grigorenko E, Picciotto M, Alberts AS, Gunel … -
DAWN: a framework to identify autism genes and subnetworks using gene expression and genetics.
Molecular autism 2014 Liu L, Lei J, Sanders SJ, Willsey AJ, Kou Y, Cicek AE, Klei L, Lu C, He X, Li M, Muhle RA, Ma'ayan A, Noonan JP, Sestan N, McFadden KA, State MW, Buxbaum JD, Devlin B, Roeder K -
Coexpression networks implicate human midfetal deep cortical projection neurons in the pathogenesis of autism.
Cell 2013 Willsey AJ, Sanders SJ, Li M, Dong S, Tebbenkamp AT, Muhle RA, Reilly SK, Lin L, Fertuzinhos S, Miller JA, Murtha MT, Bichsel C, Niu W, Cotney J, Ercan-Sencicek AG, Gockley J, Gupta AR, Han W, He X, … -
Integrated model of de novo and inherited genetic variants yields greater power to identify risk genes.
PLoS genetics 2013 He X, Sanders SJ, Liu L, De Rubeis S, Lim ET, Sutcliffe JS, Schellenberg GD, Gibbs RA, Daly MJ, Buxbaum JD, State MW, Devlin B, Roeder K -
Genetic relationship between five psychiatric disorders estimated from genome-wide SNPs.
Nature genetics 2013 Cross-Disorder Group of the Psychiatric Genomics Consortium, Lee SH, Ripke S, Neale BM, Faraone SV, Purcell SM, Perlis RH, Mowry BJ, Thapar A, Goddard ME, Witte JS, Absher D, Agartz I, Akil H, Amin F,… -
Gender differences in heterosexual college students' conceptualizations and indicators of sexual consent: implications for contemporary sexual assault prevention education.
Journal of sex research 2013 Jozkowski KN, Peterson ZD, Sanders SA, Dennis B, Reece M -
Intellectual disability is associated with increased runs of homozygosity in simplex autism.
American journal of human genetics 2013 Gamsiz ED, Viscidi EW, Frederick AM, Nagpal S, Sanders SJ, Murtha MT, Schmidt M, Simons Simplex Collection Genetics Consortium, Triche EW, Geschwind DH, State MW, Istrail S, Cook EH, Devlin B, Morrow … -
Adjusting head circumference for covariates in autism: clinical correlates of a highly heritable continuous trait.
Biological psychiatry 2013 Chaste P, Klei L, Sanders SJ, Murtha MT, Hus V, Lowe JK, Willsey AJ, Moreno-De-Luca D, Yu TW, Fombonne E, Geschwind D, Grice DE, Ledbetter DH, Lord C, Mane SM, Lese Martin C, Martin DM, Morrow EM, … -
High rate of disease-related copy number variations in childhood onset schizophrenia.
Molecular psychiatry 2013 Ahn K, Gotay N, Andersen TM, Anvari AA, Gochman P, Lee Y, Sanders S, Guha S, Darvasi A, Glessner JT, Hakonarson H, Lencz T, State MW, Shugart YY, Rapoport JL -
De novo mutations in histone-modifying genes in congenital heart disease.
Nature 2013 Zaidi S, Choi M, Wakimoto H, Ma L, Jiang J, Overton JD, Romano-Adesman A, Bjornson RD, Breitbart RE, Brown KK, Carriero NJ, Cheung YH, Deanfield J, DePalma S, Fakhro KA, Glessner J, Hakonarson H, … -
Rare complete knockouts in humans: population distribution and significant role in autism spectrum disorders.
Neuron 2013 Lim ET, Raychaudhuri S, Sanders SJ, Stevens C, Sabo A, MacArthur DG, Neale BM, Kirby A, Ruderfer DM, Fromer M, Lek M, Liu L, Flannick J, Ripke S, Nagaswamy U, Muzny D, Reid JG, Hawes A, Newsham I, Wu … -
Using whole-exome sequencing to identify inherited causes of autism.
Neuron 2013 Yu TW, Chahrour MH, Coulter ME, Jiralerspong S, Okamura-Ikeda K, Ataman B, Schmitz-Abe K, Harmin DA, Adli M, Malik AN, D'Gama AM, Lim ET, Sanders SJ, Mochida GH, Partlow JN, Sunu CM, Felie JM, … -
16p11.2.
2013 Stephan Sanders -
7q11.23 Duplications.
2013 Stephan Sanders -
Multiplex-Simplex Comparisons.
2013 Stephan Sanders -
Copy-number disorders are a common cause of congenital kidney malformations.
American journal of human genetics 2012 Sanna-Cherchi S, Kiryluk K, Burgess KE, Bodria M, Sampson MG, Hadley D, Nees SN, Verbitsky M, Perry BJ, Sterken R, Lozanovski VJ, Materna-Kiryluk A, Barlassina C, Kini A, Corbani V, Carrea A, Somenzi … -
Common genetic variants, acting additively, are a major source of risk for autism.
Molecular autism 2012 Klei L, Sanders SJ, Murtha MT, Hus V, Lowe JK, Willsey AJ, Moreno-De-Luca D, Yu TW, Fombonne E, Geschwind D, Grice DE, Ledbetter DH, Lord C, Mane SM, Martin CL, Martin DM, Morrow EM, Walsh CA, Melhem … -
Using large clinical data sets to infer pathogenicity for rare copy number variants in autism cohorts.
Molecular psychiatry 2012 Moreno-De-Luca D, Sanders SJ, Willsey AJ, Mulle JG, Lowe JK, Geschwind DH, State MW, Martin CL, Ledbetter DH -
Mutations in BCKD-kinase lead to a potentially treatable form of autism with epilepsy.
Science (New York, N.Y.) 2012 Novarino G, El-Fishawy P, Kayserili H, Meguid NA, Scott EM, Schroth J, Silhavy JL, Kara M, Khalil RO, Ben-Omran T, Ercan-Sencicek AG, Hashish AF, Sanders SJ, Gupta AR, Hashem HS, Matern D, Gabriel S, … -
Genome-wide transcriptome profiling reveals the functional impact of rare de novo and recurrent CNVs in autism spectrum disorders.
American journal of human genetics 2012 Luo R, Sanders SJ, Tian Y, Voineagu I, Huang N, Chu SH, Klei L, Cai C, Ou J, Lowe JK, Hurles ME, Devlin B, State MW, Geschwind DH -
Cytomegalovirus reactivation following autologous peripheral blood stem cell transplantation for multiple myeloma in the era of novel chemotherapeutics and tandem transplantation.
Biology of blood and marrow transplantation : journal of the American Society for Blood and Marrow Transplantation 2012 Kim JH, Goulston C, Sanders S, Lampas M, Zangari M, Tricot G, Hanson KE -
A complex chromosomal rearrangement involving chromosomes 2, 5, and X in autism spectrum disorder.
American journal of medical genetics. Part B, Neuropsychiatric genetics : the official publication of the International Society of Psychiatric Genetics 2012 Griesi-Oliveira K, Moreira Dde P, Davis-Wright N, Sanders S, Mason C, Orabona GM, Vadasz E, Bertola DR, State MW, Passos-Bueno MR -
A common X-linked inborn error of carnitine biosynthesis may be a risk factor for nondysmorphic autism.
Proceedings of the National Academy of Sciences of the United States of America 2012 Celestino-Soper PB, Violante S, Crawford EL, Luo R, Lionel AC, Delaby E, Cai G, Sadikovic B, Lee K, Lo C, Gao K, Person RE, Moss TJ, German JR, Huang N, Shinawi M, Treadwell-Deering D, Szatmari P, … -
Physiological and psychological illness symptoms at high altitude and their relationship with acute mountain sickness: a prospective cohort study.
Journal of travel medicine 2012 Oliver SJ, Sanders SJ, Williams CJ, Smith ZA, Lloyd-Davies E, Roberts R, Arthur C, Hardy L, Macdonald JH -
De novo mutations revealed by whole-exome sequencing are strongly associated with autism.
Nature 2012 Sanders SJ, Murtha MT, Gupta AR, Murdoch JD, Raubeson MJ, Willsey AJ, Ercan-Sencicek AG, DiLullo NM, Parikshak NN, Stein JL, Walker MF, Ober GT, Teran NA, Song Y, El-Fishawy P, Murtha RC, Choi M, … -
A balanced t(10;15) translocation in a male patient with developmental language disorder.
European journal of medical genetics 2011 Ercan-Sencicek AG, Davis Wright NR, Sanders SJ, Oakman N, Valdes L, Bakkaloglu B, Doyle N, Yrigollen CM, Morgan TM, Grigorenko EL -
Searching for Potocki-Lupski syndrome phenotype: a patient with language impairment and no autism.
Brain & development 2011 Gulhan Ercan-Sencicek A, Davis Wright NR, Frost SJ, Fulbright RK, Felsenfeld S, Hart L, Landi N, Einar Mencl W, Sanders SJ, Pugh KR, State MW, Grigorenko EL -
Rare copy number variants in tourette syndrome disrupt genes in histaminergic pathways and overlap with autism.
Biological psychiatry 2011 Fernandez TV, Sanders SJ, Yurkiewicz IR, Ercan-Sencicek AG, Kim YS, Fishman DO, Raubeson MJ, Song Y, Yasuno K, Ho WS, Bilguvar K, Glessner J, Chu SH, Leckman JF, King RA, Gilbert DL, Heiman GA, … -
Use of array CGH to detect exonic copy number variants throughout the genome in autism families detects a novel deletion in TMLHE.
Human molecular genetics 2011 Celestino-Soper PB, Shaw CA, Sanders SJ, Li J, Murtha MT, Ercan-Sencicek AG, Davis L, Thomson S, Gambin T, Chinault AC, Ou Z, German JR, Milosavljevic A, Sutcliffe JS, Cook EH, Stankiewicz P, State MW… -
Multiple recurrent de novo CNVs, including duplications of the 7q11.23 Williams syndrome region, are strongly associated with autism.
Neuron 2011 Sanders SJ, Ercan-Sencicek AG, Hus V, Luo R, Murtha MT, Moreno-De-Luca D, Chu SH, Moreau MP, Gupta AR, Thomson SA, Mason CE, Bilguvar K, Celestino-Soper PB, Choi M, Crawford EL, Davis L, Wright NR, … -
Deletion 17q12 Is a Recurrent Copy Number Variant that Confers High Risk of Autism and Schizophrenia.
The American Journal of Human Genetics 2011 Daniel Moreno-De-Luca, SGENE Consortium, Jennifer G. Mulle, Simons Simplex Collection Genetics Consortium, Erin B. Kaminsky, Stephan J. Sanders, GeneSTAR, Scott M. Myers, Margaret P. Adam, Amy T. … -
Deletion 17q12 is a recurrent copy number variant that confers high risk of autism and schizophrenia.
American journal of human genetics 2010 Moreno-De-Luca D, SGENE Consortium, Mulle JG, Simons Simplex Collection Genetics Consortium, Kaminsky EB, Sanders SJ, GeneSTAR, Myers SM, Adam MP, Pakula AT, Eisenhauer NJ, Uhas K, Weik L, Guy L, Care… -
Sexual behavior in the United States: results from a national probability sample of men and women ages 14-94.
The journal of sexual medicine 2010 Herbenick D, Reece M, Schick V, Sanders SA, Dodge B, Fortenberry JD -
Whole-exome sequencing identifies recessive WDR62 mutations in severe brain malformations.
Nature 2010 Bilgüvar K, Oztürk AK, Louvi A, Kwan KY, Choi M, Tatli B, Yalnizoglu D, Tüysüz B, Caglayan AO, Gökben S, Kaymakçalan H, Barak T, Bakircioglu M, Yasuno K, Ho W, Sanders S, Zhu Y, Yilmaz S, Dinçer A, … -
L-histidine decarboxylase and Tourette's syndrome.
The New England journal of medicine 2010 Ercan-Sencicek AG, Stillman AA, Ghosh AK, Bilguvar K, O'Roak BJ, Mason CE, Abbott T, Gupta A, King RA, Pauls DL, Tischfield JA, Heiman GA, Singer HS, Gilbert DL, Hoekstra PJ, Morgan TM, Loring E, … -
Standardizing the next generation of bioinformatics software development with BioHDF (HDF5).
Advances in experimental medicine and biology 2010 Mason CE, Zumbo P, Sanders S, Folk M, Robinson D, Aydt R, Gollery M, Welsh M, Olson NE, Smith TM -
Body composition at high altitude: a randomized placebo-controlled trial of dietary carbohydrate supplementation.
The American journal of clinical nutrition 2009 Macdonald JH, Oliver SJ, Hillyer K, Sanders S, Smith Z, Williams C, Yates D, Ginnever H, Scanlon E, Roberts E, Murphy D, Lawley J, Chichester E -
Condom use as a dependent variable: a brief commentary about classification of inconsistent users.
AIDS and behavior 2004 Crosby RA, Yarber WL, Sanders SA, Graham CA -
Hereditary hyperferritinaemia-cataract syndrome and differential diagnosis of hereditary haemochromatosis.
Postgraduate medical journal 2003 Sanders SJ, Suri M, Ross I -
Appositions between cocaine and amphetamine-related transcript- and gonadotropin releasing hormone-immunoreactive neurons in the hypothalamus of the Siberian hamster.
Neuroscience letters 2001 Leslie RA, Sanders SJ, Anderson SI, Schuhler S, Horan TL, Ebling FJ